U.S. flag

An official website of the United States government

Format

Send to:

Choose Destination

Phosphaturic mesenchymal tumor

MedGen UID:
371179
Concept ID:
C1831619
Neoplastic Process
Synonyms: Phosphaturic Mesenchymal Tumor; phosphaturic mesenchymal tumor; Phosphaturic Mesenchymal Tumor, Mixed Connective Tissue Type; phosphaturic mesenchymal tumor, mixed connective tissue type; Phosphaturic Mesenchymal Tumor, Mixed Connective Tissue Variant; phosphaturic mesenchymal tumor, mixed connective tissue variant
 
HPO: HP:0033987
Monarch Initiative: MONDO:0006368

Definition

A rare, endocrine active tumor that causes severe renal phosphate wasting, which in turn can lead to critical osteomalacia. Phosphaturic mesenchymal tumors (PMTs) are typically small and mostly benign tumors producing fibroblast growth factor 23 (FGF-23). FGF-23 lowers the expression of sodium/phosphate cotransporters, which are the primary transport proteins responsible for phosphate reabsorption in the kidneys. The paraneoplastic overproduction of FGF-23 lowers reabsorption of phosphate and causes severe paraneoplastic renal phosphate wasting and hypophosphatemia. FGF-23 also affects vitamin D levels by lowering 25-hydroxyvitamin D 1-alpha-hydroxylase in the proximal renal tubules and by increasing the expression of vitamin D 24-hydroxylase, a mitochondrial enzyme responsible for inactivating vitamin D metabolites. [from HPO]

Term Hierarchy

Professional guidelines

PubMed

Hacisahinogullari H, Tekin S, Tanrikulu S, Saribeyliler G, Yalin GY, Bilgic B, Isik EG, Salduz A, Tuncer S, Gul N, Uzum AK, Aral F, Tanakol R, Selcukbiricik OS
Endocrine 2023 Nov;82(2):427-434. Epub 2023 Jul 22 doi: 10.1007/s12020-023-03450-3. PMID: 37480497
Strobel K, Exner UE, Stumpe KD, Hany TF, Bode B, Mende K, Veit-Haibach P, von Schulthess GK, Hodler J
Eur J Nucl Med Mol Imaging 2008 Nov;35(11):2000-8. Epub 2008 Aug 20 doi: 10.1007/s00259-008-0876-0. PMID: 18712385

Recent clinical studies

Etiology

Parameshwar VC, Rekhi B, Duggad A, Ramadwar M
Indian J Pathol Microbiol 2024 Apr 1;67(2):306-311. Epub 2023 Nov 9 doi: 10.4103/ijpm.ijpm_295_23. PMID: 38394416
Abate V, Vergatti A, De Filippo G, Damiano V, Menale C, D'Elia L, Rendina D
J Clin Endocrinol Metab 2024 Feb 20;109(3):e1006-e1011. doi: 10.1210/clinem/dgad690. PMID: 38006315
Hacisahinogullari H, Tekin S, Tanrikulu S, Saribeyliler G, Yalin GY, Bilgic B, Isik EG, Salduz A, Tuncer S, Gul N, Uzum AK, Aral F, Tanakol R, Selcukbiricik OS
Endocrine 2023 Nov;82(2):427-434. Epub 2023 Jul 22 doi: 10.1007/s12020-023-03450-3. PMID: 37480497
Wu H, Bui MM, Zhou L, Li D, Zhang H, Zhong D
Mod Pathol 2019 Feb;32(2):189-204. Epub 2018 Sep 11 doi: 10.1038/s41379-018-0100-0. PMID: 30206408
Hautmann AH, Hautmann MG, Kölbl O, Herr W, Fleck M
Curr Rheumatol Rep 2015 Jun;17(6):512. doi: 10.1007/s11926-015-0512-5. PMID: 25900190

Diagnosis

Hacisahinogullari H, Tekin S, Tanrikulu S, Saribeyliler G, Yalin GY, Bilgic B, Isik EG, Salduz A, Tuncer S, Gul N, Uzum AK, Aral F, Tanakol R, Selcukbiricik OS
Endocrine 2023 Nov;82(2):427-434. Epub 2023 Jul 22 doi: 10.1007/s12020-023-03450-3. PMID: 37480497
Benson JC, Trejo-Lopez JA, Nassiri AM, Eschbacher K, Link MJ, Driscoll CL, Tiegs RD, Sfeir J, DeLone DR
AJNR Am J Neuroradiol 2022 Jun;43(6):817-822. Epub 2022 May 19 doi: 10.3174/ajnr.A7513. PMID: 35589138Free PMC Article
Sumathi VP
Surg Pathol Clin 2021 Dec;14(4):737-750. Epub 2021 Oct 7 doi: 10.1016/j.path.2021.06.013. PMID: 34742491
Xiao X, Sun X, Ni P, Huang Y, Xie T
Medicine (Baltimore) 2018 Oct;97(40):e12507. doi: 10.1097/MD.0000000000012507. PMID: 30290606Free PMC Article
Boland JM, Tebben PJ, Folpe AL
J Endocrinol Invest 2018 Oct;41(10):1173-1184. Epub 2018 Feb 14 doi: 10.1007/s40618-018-0849-5. PMID: 29446010

Therapy

Das O, Mohin M, Dey S, Kar A, Singhania P, Adhikari S, Chowdhury S, Chatterjee U
Diagn Cytopathol 2024 Feb;52(2):E44-E47. Epub 2023 Oct 28 doi: 10.1002/dc.25245. PMID: 37897246
Zhang Y, Wang P, Jing H
Clin Nucl Med 2023 Sep 1;48(9):826-827. Epub 2023 Jul 22 doi: 10.1097/RLU.0000000000004771. PMID: 37486706
Palmerini E, Seeger LL, Gambarotti M, Righi A, Reichardt P, Bukata S, Blay JY, Dai T, Jandial D, Picci P
BMC Cancer 2021 Jan 22;21(1):89. doi: 10.1186/s12885-020-07739-8. PMID: 33482769Free PMC Article
Xian MF, Pan KM, Zhang JC, Cheng MQ, Huang H, Chen LD, Zhao ZX, Wang W
Clin Hemorheol Microcirc 2021;77(1):61-69. doi: 10.3233/CH-200921. PMID: 32924995
Boland JM, Tebben PJ, Folpe AL
J Endocrinol Invest 2018 Oct;41(10):1173-1184. Epub 2018 Feb 14 doi: 10.1007/s40618-018-0849-5. PMID: 29446010

Prognosis

Argersinger DP, Haring CT, Hanks JE, Kovatch KJ, Ali SA, McHugh JB, Pynnonen MA, McKean EL
Ann Otol Rhinol Laryngol 2022 Jun;131(6):647-654. Epub 2021 Aug 8 doi: 10.1177/00034894211037416. PMID: 34369202
Liu S, Zhou X, Song A, Huo Z, Wang Y, Xia W, Liu Y
Medicine (Baltimore) 2019 Jul;98(27):e16296. doi: 10.1097/MD.0000000000016296. PMID: 31277164Free PMC Article
Hautmann AH, Hautmann MG, Kölbl O, Herr W, Fleck M
Curr Rheumatol Rep 2015 Jun;17(6):512. doi: 10.1007/s11926-015-0512-5. PMID: 25900190
Hu FK, Yuan F, Jiang CY, Lv DW, Mao BB, Zhang Q, Yuan ZQ, Wang Y
Chin J Cancer 2011 Nov;30(11):794-804. doi: 10.5732/cjc.011.10013. PMID: 22035861Free PMC Article
Siegel HJ, Rock MG, Inwards C, Sim FH
Orthopedics 2002 Nov;25(11):1279-81. doi: 10.3928/0147-7447-20021101-21. PMID: 12452347

Clinical prediction guides

Mazza M, Arcidiacono GP, Hoxhaj I, Padoan V, Tasca G, Burei M, Sella S, Simioni P, Giannini S, Mocellin S
Calcif Tissue Int 2024 Aug;115(2):196-203. Epub 2024 May 28 doi: 10.1007/s00223-024-01231-2. PMID: 38806758Free PMC Article
Parameshwar VC, Rekhi B, Duggad A, Ramadwar M
Indian J Pathol Microbiol 2024 Apr 1;67(2):306-311. Epub 2023 Nov 9 doi: 10.4103/ijpm.ijpm_295_23. PMID: 38394416
Kato A, Nakamoto Y, Ishimori T, Hayakawa N, Ueda M, Temma T, Sano K, Shimizu Y, Saga T, Togashi K
Ann Nucl Med 2021 Mar;35(3):397-405. Epub 2021 Feb 13 doi: 10.1007/s12149-021-01575-x. PMID: 33582980
Villepelet A, Casiraghi O, Temam S, Moya-Plana A
Eur Ann Otorhinolaryngol Head Neck Dis 2018 Oct;135(5):365-369. Epub 2018 Jul 17 doi: 10.1016/j.anorl.2018.07.001. PMID: 30026073
Tajima S, Takashi Y, Ito N, Fukumoto S, Fukuyama M
Med Mol Morphol 2016 Dec;49(4):203-209. Epub 2015 Jun 30 doi: 10.1007/s00795-015-0115-2. PMID: 26122367

Recent systematic reviews

Sánchez Muñoz R, Sanmillan JL, Vidal Sarró N, Martín Quintero G, Martí Duce D, Gabarrós Canals A
World Neurosurg 2024 Jul;187:70-81. Epub 2024 Mar 30 doi: 10.1016/j.wneu.2024.03.138. PMID: 38561034
Chen D, Zhang L, Zhang J, Yin M, Gao X, Huang Q, Li L, Yang X
World Neurosurg 2024 Apr;184:65-73. Epub 2024 Jan 12 doi: 10.1016/j.wneu.2024.01.032. PMID: 38218444
Abate V, Vergatti A, De Filippo G, Damiano V, Menale C, D'Elia L, Rendina D
J Clin Endocrinol Metab 2024 Feb 20;109(3):e1006-e1011. doi: 10.1210/clinem/dgad690. PMID: 38006315
Wang X, Gao J, Han S, Li Y
J Clin Neurosci 2019 May;63:234-239. Epub 2019 Jan 17 doi: 10.1016/j.jocn.2019.01.010. PMID: 30660478
Meng T, Zhou W, Li B, Yin H, Li Z, Zhou L, Kong J, Yan W, Yang X, Liu T, Song D, Xiao J
World J Surg Oncol 2015 May 8;13:176. doi: 10.1186/s12957-015-0589-3. PMID: 25951872Free PMC Article

Supplemental Content

Table of contents

    Clinical resources

    Practice guidelines

    • PubMed
      See practice and clinical guidelines in PubMed. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.
    • Bookshelf
      See practice and clinical guidelines in NCBI Bookshelf. The search results may include broader topics and may not capture all published guidelines. See the FAQ for details.

    Consumer resources

    Recent activity

    Your browsing activity is empty.

    Activity recording is turned off.

    Turn recording back on

    See more...