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Hypoparathyroidism, familial isolated, 2(FIH2)

MedGen UID:
1715177
Concept ID:
C5394383
Disease or Syndrome
Synonyms: FIH2; HYPOPARATHYROIDISM, FAMILIAL ISOLATED, 2
 
Gene (location): GCM2 (6p24.2)
 
Monarch Initiative: MONDO:0020798
OMIM®: 618883

Definition

Patients with familial isolated hypoparathyroidism-2 (FIH2) usually present with seizures, caused by hypocalcemia, in early life. Serum parathyroid hormone (PTH; 168450) levels are low to undetectable. Hyperphosphatemia is present, and levels of 25-hydroxyvitamin D and 1,25-dihydroxyvitamin D may be within the normal range. Development can be normal if hypocalcemia is treated with calcium and vitamin D supplementation (Ding et al., 2001). Some patients have been found to lack parathyroid glands (Thomee et al., 2005). For a discussion of genetic heterogeneity of familial isolated hypoparathyroidism, see FIH1 (146200). [from OMIM]

Clinical features

From HPO
Hypocalcemic seizures
MedGen UID:
340985
Concept ID:
C1855841
Disease or Syndrome
Hypocalcemia
MedGen UID:
5705
Concept ID:
C0020598
Disease or Syndrome
An abnormally decreased calcium concentration in the blood.
Hyperphosphatemia
MedGen UID:
39326
Concept ID:
C0085681
Disease or Syndrome
An abnormally increased phosphate concentration in the blood.
Decreased circulating parathyroid hormone level
MedGen UID:
1630961
Concept ID:
C0729198
Finding
An abnormally decreased concentration of parathyroid hormone.

Recent clinical studies

Etiology

Park SY, Eom YS, Choi B, Yi HS, Yu SH, Lee K, Jin HS, Chung YS, Jung TS, Lee S
J Korean Med Sci 2013 Oct;28(10):1489-95. Epub 2013 Sep 25 doi: 10.3346/jkms.2013.28.10.1489. PMID: 24133354Free PMC Article

Diagnosis

Hawkes CP, Al Jubeh JM, Li D, Tucker SE, Rajiyah T, Levine MA
J Clin Endocrinol Metab 2022 May 17;107(6):e2449-e2458. doi: 10.1210/clinem/dgac086. PMID: 35165722Free PMC Article
Cinque L, Sparaneo A, Penta L, Mencarelli A, Rogaia D, Esposito S, Fabrizio FP, Baorda F, Verrotti A, Falorni A, Stangoni G, Hendy GN, Guarnieri V, Prontera P
J Clin Endocrinol Metab 2017 Nov 1;102(11):3961-3969. doi: 10.1210/jc.2017-00250. PMID: 28938448
Park SY, Eom YS, Choi B, Yi HS, Yu SH, Lee K, Jin HS, Chung YS, Jung TS, Lee S
J Korean Med Sci 2013 Oct;28(10):1489-95. Epub 2013 Sep 25 doi: 10.3346/jkms.2013.28.10.1489. PMID: 24133354Free PMC Article

Prognosis

Cinque L, Sparaneo A, Penta L, Mencarelli A, Rogaia D, Esposito S, Fabrizio FP, Baorda F, Verrotti A, Falorni A, Stangoni G, Hendy GN, Guarnieri V, Prontera P
J Clin Endocrinol Metab 2017 Nov 1;102(11):3961-3969. doi: 10.1210/jc.2017-00250. PMID: 28938448
Yi HS, Eom YS, Park IeB, Lee S, Hong S, Jüppner H, Mannstadt M, Lee S
Clin Endocrinol (Oxf) 2012 May;76(5):625-33. doi: 10.1111/j.1365-2265.2011.04256.x. PMID: 22066718Free PMC Article

Clinical prediction guides

Cinque L, Sparaneo A, Penta L, Mencarelli A, Rogaia D, Esposito S, Fabrizio FP, Baorda F, Verrotti A, Falorni A, Stangoni G, Hendy GN, Guarnieri V, Prontera P
J Clin Endocrinol Metab 2017 Nov 1;102(11):3961-3969. doi: 10.1210/jc.2017-00250. PMID: 28938448
Yi HS, Eom YS, Park IeB, Lee S, Hong S, Jüppner H, Mannstadt M, Lee S
Clin Endocrinol (Oxf) 2012 May;76(5):625-33. doi: 10.1111/j.1365-2265.2011.04256.x. PMID: 22066718Free PMC Article

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