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Mosaic variegated aneuploidy syndrome

MedGen UID:
1641418
Concept ID:
C4551972
Disease or Syndrome
Synonym: MVA syndrome
SNOMED CT: Mosaic variegated aneuploidy syndrome (700056005)
Modes of inheritance:
Autosomal recessive inheritance
MedGen UID:
141025
Concept ID:
C0441748
Intellectual Product
Source: Orphanet
A mode of inheritance that is observed for traits related to a gene encoded on one of the autosomes (i.e., the human chromosomes 1-22) in which a trait manifests in individuals with two pathogenic alleles, either homozygotes (two copies of the same mutant allele) or compound heterozygotes (whereby each copy of a gene has a distinct mutant allele).
Autosomal dominant inheritance
MedGen UID:
141047
Concept ID:
C0443147
Intellectual Product
Source: Orphanet
A mode of inheritance that is observed for traits related to a gene encoded on one of the autosomes (i.e., the human chromosomes 1-22) in which a trait manifests in heterozygotes. In the context of medical genetics, an autosomal dominant disorder is caused when a single copy of the mutant allele is present. Males and females are affected equally, and can both transmit the disorder with a risk of 50% for each child of inheriting the mutant allele.
 
Related genes: CEP57, TRIP13, BUB1B
 
Monarch Initiative: MONDO:0000141
OMIM® Phenotypic series: PS257300
Orphanet: ORPHA1052

Definition

Mosaic variegated aneuploidy (MVA) is an autosomal recessive disorder characterized by mosaic aneuploidies, predominantly trisomies and monosomies, involving multiple different chromosomes and tissues. The proportion of aneuploid cells varies but is usually more than 25% and is substantially greater than in normal individuals. Affected individuals typically present with severe intrauterine growth retardation and microcephaly. Eye anomalies, mild dysmorphism, variable developmental delay, and a broad spectrum of additional congenital abnormalities and medical conditions may also occur. The risk of malignancy is high, with rhabdomyosarcoma, Wilms tumor, and leukemia reported in several cases (summary by Hanks et al., 2004). Genetic Heterogeneity of Mosaic Variegated Aneuploidy Syndrome See also MVA2 (614114), caused by mutation in the CEP57 gene (607951) on chromosome 11q21; MVA3 (617598), caused by mutation in the TRIP13 gene (604507) on chromosome 5p15; MVA4 (620153), caused by mutation in the CENATAC gene (620142) on chromosome 11q23; MVA5 (620184), caused by mutation in the SLF2 gene (610348) on chromosome 10q24; and MVA6 (620185), caused by mutation in the SMC5 gene (609386) on chromosome 9q21. [from OMIM]

Professional guidelines

PubMed

Levy B, Hoffmann ER, McCoy RC, Grati FR
Prenat Diagn 2021 Apr;41(5):631-641. Epub 2021 Mar 22 doi: 10.1002/pd.5931. PMID: 33720449Free PMC Article

Recent clinical studies

Etiology

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Diagnosis

Levy B, Hoffmann ER, McCoy RC, Grati FR
Prenat Diagn 2021 Apr;41(5):631-641. Epub 2021 Mar 22 doi: 10.1002/pd.5931. PMID: 33720449Free PMC Article
Yamaguchi T, Yamaguchi M, Akeno K, Fujisaki M, Sumiyoshi K, Ohashi M, Sameshima H, Ozaki M, Kato M, Kato T, Hosoba E, Kurahashi H
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Therapy

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Prognosis

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Clinical prediction guides

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